Cell Reports · 2014 · 62 citations · 28 references
Life SciencesGeneticsMolecular GeneticsAutoimmunityDna RepairGene ExpressionAutoimmune Disease Susceptibility GenesAutoimmune DiseasesDna Polymerase FunctionPolymerase Chain ReactionSomatic HypermutationSystemic Lupus ErythematosusAssociation Study ReplicationBase Excision Repair DefectsDna Polymerase BetaHypomorphic AllelesImmunoglobulin Heavy Chain LocusSomatic Hypermutation In AutoimmunitySystemic Lupus Erythematosus AssociationsSystemic Lupus Erythematosus Models
A replication study of a previous genome-wide association study (GWAS) suggested that a SNP linked to the POLB gene is associated with systemic lupus erythematosus (SLE). This SNP is correlated with decreased expression of Pol β, a key enzyme in the base excision repair (BER) pathway. To determine whether decreased Pol β activity results in SLE, we constructed a mouse model of POLB that encodes an enzyme with slow DNA polymerase activity. We show that mice expressing this hypomorphic POLB allele develop an autoimmune pathology that strongly resembles SLE. Of note, the mutant mice have shorter immunoglobulin heavy-chain junctions and somatic hypermutation is dramatically increased. These results demonstrate that decreased Pol β activity during the generation of immune diversity leads to lupus-like disease in mice, and suggest that decreased expression of Pol β in humans is an underlying cause of SLE.
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