Science · 2001 · 2.2K citations · 18 references
Life SciencesBiochemistryMolecular BiologyApoptosisCell DivisionNeurodegenerationNeurodegenerative DiseasesNeurodegenerative DisordersProtein AggregationProtein Aggregation DisordersProtein DegradationProtein MisfoldingCell Division ControlHuntingtin AggregationPolyglutamine DiseasesProtein AggregatesTransient ExpressionUbiquitin-mediated DegradationUbiquitin-mediated ProteolysisUbiquitin-proteasome System Dysfunction
Intracellular deposition of aggregated and ubiquitylated proteins is a prominent cytopathological feature of most neurodegenerative disorders. Whether protein aggregates themselves are pathogenic or are the consequence of an underlying molecular lesion is unclear. Here, we report that protein aggregation directly impaired the function of the ubiquitin-proteasome system. Transient expression of two unrelated aggregation-prone proteins, a huntingtin fragment containing a pathogenic polyglutamine repeat and a folding mutant of cystic fibrosis transmembrane conductance regulator, caused nearly complete inhibition of the ubiquitin-proteasome system. Because of the central role of ubiquitin-dependent proteolysis in regulating fundamental cellular events such as cell division and apoptosis, our data suggest a potential mechanism linking protein aggregation to cellular disregulation and cell death.
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Identification of genes that modify ataxin-1-induced neurodegeneration
Pedro Fernández-Fúnez, María Laura Niño-Rosales, Béatrice Gouyon et al. · Nature · 2000 · 662 citations