A histone deacetylase 3 and mitochondrial complex I axis regulates toxic formaldehyde production

Niek Wit, Ewa Gogola, James A. West, Tristan Vornbäumen, Rachel Seear, Peter S. J. Bailey, Guillermo Burgos-Barragan, Meng Wang, Patrycja A. Krawczyk, Daphne H. E. W. Huberts,

Science Advances · 2023 · 20 citations · 41 references

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Abstract

Cells produce considerable genotoxic formaldehyde from an unknown source. We carry out a genome-wide CRISPR-Cas9 genetic screen in metabolically engineered HAP1 cells that are auxotrophic for formaldehyde to find this cellular source. We identify histone deacetylase 3 (HDAC3) as a regulator of cellular formaldehyde production. HDAC3 regulation requires deacetylase activity, and a secondary genetic screen identifies several components of mitochondrial complex I as mediators of this regulation. Metabolic profiling indicates that this unexpected mitochondrial requirement for formaldehyde detoxification is separate from energy generation. HDAC3 and complex I therefore control the abundance of a ubiquitous genotoxic metabolite.

References

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