Genetics and Molecular Biology · 2016 · 26 citations · 17 references
Life SciencesGeneticsMolecular GeneticsCancer GeneticsMedical GeneticsMolecular OncologyCancer Molecular DiagnosticsGermline Cancer PredispositionGermline Cancer SusceptibilityHereditary Cancer SyndromesMutation AnalysisOncogene MutationsGermline Cancer Predisposition SyndromesGermline Mutation AnalysisGermline Mutation TestingHereditary Breast Cancer SyndromeInherited Cancer RiskLi-fraumeni SyndromeTp53 MutationsTumor Mutation Analysis
Germline TP53 mutations are associated with Li-Fraumeni syndrome (LFS), a disease that predisposes carriers to a wide variety of early onset tumors. In southern and southeastern Brazil, a high frequency of a germline TP53 mutation, p.R337H, was diagnosed in 0,3% of the population due to a founder effect. Carriers are at risk for developing cancer but the penetrance is lower than in typical DNA binding domain mutations. To date, only a few families were detected and diagnosis of carriers remains a challenge. Therefore, the inclusion of additional criteria to detect p.R337H carriers is necessary for the Brazilian population. We assessed the A.C. Camargo Cancer Center Oncogenetics Department database in search of common characteristics associated with p.R337H families that did not fulfill LFS/LFL clinical criteria. Among 42 p.R337H families, three did not meet any LFS/LFL criteria. All cases were young female patients with breast cancer diagnosed before age 45 and with no family history of LFS linked-cancers. Our results suggest that screening for the germline TP53 p.R337H mutation should be indicated, along with BRCA1 and BRCA2 genetic testing, for this group of patients, especially in the South and Southeast of Brazil.
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Germ Line p53 Mutations in a Familial Syndrome of Breast Cancer, Sarcomas, and Other Neoplasms
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Life Sciences, Genetics, Oncology +17
Soft-Tissue Sarcomas, Breast Cancer, and Other Neoplasms
Frederick P. Li · Annals of Internal Medicine · 1969 · 1.5K citations
Prevalence and diversity of constitutional mutations in the p53 gene among 21 Li-Fraumeni families
Birch, Hartley, Tricker et al. · Cancer Research · 1994 · 478 citations
Prevalence and diversity of constitutional mutations in the p53 gene among 21 Li-Fraumeni families.
John Birch, Alison Condie, AM Kelsey et al. · PubMed · 1994 · 425 citations
Life Sciences, Genetics, Oncology +17