Proceedings of the National Academy of Sciences · 1989 · 99 citations · 26 references
Life SciencesNeurobiologyNeuroscienceMolecular NeurobiologyMolecular NeuroscienceNeurogeneticsDemyelinating DiseasesDemyelinating DisordersNervous TissueOligodendrocyte BiologyProtein SynthesisRodent NeurologyHypomyelinating DisordersMyelin BiologyMyelin FormationMyelin ProteinsMyelin-associated ProteinsPromoter ControlTransgenic MiceTransgenic Mouse Models
A minigene containing mouse cDNA coding for the smallest type of myelin basic protein and including the native promoter was constructed and used to produce transgenic shiverer mice. The hypomyelinating mouse, the shiverer, has a deletion in its myelin basic protein gene, lacks all four types of myelin basic protein in its myelin, and shows abnormal behavior such as violent tremors. Five of twenty-one transgenic shiverer mice showed recovered protein synthesis, compact myelin formation, and normal behavior. These results suggest that a single type of myelin basic protein restores myelin formation and returns the shivering phenotype to normal in the transgenic shiverer mouse.
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