Determining the Pathogenicity of a Genomic Variant of Uncertain Significance Using CRISPR/Cas9 and Human-Induced Pluripotent Stem Cells

Joe Z. Zhang, Ilanit Itzhaki, Sophia Zhang, Haodong Chen, François Haddad, Tomoya Kitani, Kitchener D. Wilson, Lei Tian, Rajani Shrestha, Haodi Wu,

Circulation · 2018 · 142 citations · 36 references

DOIFull text

Open access

Abstract

Our study illustrates the ability of clustered regularly interspaced short palindromic repeats/Cas9 genome-editing of carrier-specific iPSCs to elucidate both benign and pathogenic HCM functional phenotypes in a carrier-specific manner in a dish. As such, this platform represents a promising VUS risk-assessment tool that can be used for assessing HCM-associated VUS specifically, and VUS in general, and thus significantly contribute to the arsenal of precision medicine tools available in this emerging field.

References

36