Journal of Pediatric Hematology/Oncology · 1999 · 31 citations · 13 references
MedicineOncologyPathologyMedical OncologyMolecular OncologyNeoplasiaCutaneous NeoplasmsMalignant NeoplasmsMalignant TumorsPediatric SarcomasPediatric TumorsSoft Tissue SarcomasCardio-dermatologic SyndromesEmbryonal RhabdomyosarcomaNeurofibromatosis Type 1Neurofibromatosis-associated TumorsPulmonary Valve StenosisRhabdomyosarcoma BiologySarcoma PathologySoft Tissue Sarcoma Histopathology
A boy with characteristic facial features, pulmonary valvular stenosis, ectodermal abnormalities, growth failure, and mental retardation was admitted for intestinal occlusion at 20 months of age. Clinical findings were consistent with a diagnosis of cardio-facio-cutaneous syndrome (CFC-s), and a huge abdominal mass was evident on computed tomography scan. A biopsy was performed, and embryonal rhabdomyosarcoma was diagnosed. Molecular analysis was performed by reverse transcription (RT) polymerase chain reaction (PCR) on tumor RNA to seek the chimerical transcript of the most common soft tissue sarcoma translocations and analyze neurofibromatosis 1 (NF1) gene expression. Translocations involving 1;13, 2;13, and 11;22 were not found, and the specific transcripts of the NF1 gene were present. Chemotherapy was implemented, but the child died 7 months later of tumor progression. Few patients with CFC-s have been described, and their follow-up is not well known. The association of CFC-s with rhabdomyosarcoma has not been reported previously, but other neoplasms have been reported in patients with Noonan syndrome, a condition similar to CFC-s. More observations are needed, but this and other reports suggest there could be a higher risk of malignancy in patients with syndromes in the Noonan phenotype category.
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Mapping a gene for Noonan syndrome to the long arm of chromosome 12
C. Ruth Jamieson, Ineke van der Burgt, Angela F. Brady et al. · Nature Genetics · 1994 · 290 citations
The epidemiology of soft tissue sarcoma.
Shelia Hoar Zahm, J F Fraumeni · PubMed · 1997 · 239 citations
Neurofibromatosis type 1 and childhood cancer
Ichiro Matsui, Masako Tanimura, Noboru Kobayashi et al. · Cancer · 1993 · 191 citations · Full text
Medicine, Oncology, Pediatrics +11
Occurrence of myeloproliferative disorder in patients with Noonan syndrome
Brigitte Bader‐Meunier, Gil Tchernia, F Miélot et al. · The Journal of Pediatrics · 1997 · 179 citations
Medicine, Hematology, Pathology +5