Molecular Endocrinology · 1995 · 97 citations · 11 references
Life SciencesDevelopmental BiologyGeneticsGene ExpressionReproductive EndocrinologySteroid BiochemistryAdrenal Steroid HormonesGonadal HormonesGonadal Steroid HormonesMammalian EndocrinologyNuclear ReceptorsSteroidogenesis GeneticsDevelopmental Regulation Of SteroidogenesisDevelopmental SteroidogenesisGlucocorticoid ReceptorsMale DifferentiationSteroidogenic Factor 1Steroidogenic Gene ExpressionSteroidogenic Transcription Factors
Targeted disruption of the mouse Ftz-F1 gene, which encodes the orphan nuclear receptors steroidogenic factor 1 (SF-1) and embryonal long terminal repeat-binding protein (ELP), established that this gene is essential for development of the primary steroidogenic tissues and for male sexual differentiation. Associated with these dramatic developmental abnormalities, all Ftz-F1-disrupted mice died in the immediate postnatal period and had very low glucocorticoid levels. In this report, we show that treatment with corticosteroids markedly prolonged survival of the Ftz-F1-disrupted mice, proving that steroid hormone deficiency causes their death. We also generated SF-1-specific knockout mice with a targeting construct that specifically disrupted the SF-1 coding sequence without impairing the ELP protein. The phenotype of the SF-1-specific knockout mice was indistinguishable from that observed in Ftz-F1-disrupted mice that lack both SF-1 and ELP. Taken together, these results indicate that SF-1 is the Ftz-F1-encoded protein that is required for multiple aspects of endocrine development and for postnatal survival.
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The nuclear receptor steroidogenic factor 1 acts at multiple levels of the reproductive axis.
Holly A. Ingraham, Deepak S. Lala, Yayoi Ikeda et al. · Genes & Development · 1994 · 611 citations · Full text
Medicine, Endocrinology, Genetics +17