Muscle & Nerve · 1995 · 12 citations · 8 references
Life SciencesGeneticsMolecular GeneticsHuman GeneticsMitochondrial BiologyMitochondrial GeneticsMitochondrial BiochemistryMitochondrial DiseaseMitochondrial DisordersMitochondrial DysfunctionMitochondrial PhysiologyMitochondrial TranslationMitochondrial Dna MutationsMitochondrial Respiratory Chain DefectsMitochondrial SyndromesPearson SyndromeRespiratory Chain Complex DeficienciesRespiratory Chain DeficiencyRespiratory Chain DysfunctionTissue-specific Expression
Pearson syndrome is a fatal disorder involving the hematopoietic system and exocrine pancreas. Mitochondrial respiratory chain deficiencies and/or rearrangements of the mitochondrial DNA were consistently observed in all patients. We report here on the variant phenotypic expression of mitochondrial genotypes in cultured cells from a patient with Pearson syndrome. Skin fibroblasts and lymphocytes harbored, respectively, 60% and 80% of deleted mtDNA molecules initially and displayed defective respiratory chain activities. In both cases, there was a progressive recovery of respiratory chain activities during in vitro cell proliferation due to the loss of deleted mtDNA molecules in cultured skin fibroblasts and to an increase in the mtRNA translation efficiency in Epstein-Barr virus-transformed lymphocytes. The present study suggests that various cellular responses to abnormal mitochondrial genotypes might contribute to the tissue-specific expression of mitochondrial disorders in vivo.
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URF6, Last Unidentified Reading Frame of Human mtDNA, Codes for an NADH Dehydrogenase Subunit
Anne Chomyn, Michael W. J. Cleeter, CI Ragan et al. · Science · 1986 · 345 citations
Pearson syndrome and mitochondrial encephalomyopathy in a patient with a deletion of mtDNA.
M A McShane, Simon Hammans, M G Sweeney et al. · PubMed · 1991 · 255 citations