Science · 1985 · 75 citations · 12 references
Life SciencesGeneticsMolecular GeneticsHuman GeneticsMedical GeneticsNeurogeneticsFamily-based Genetic AnalysisGenetic DisordersGenetic LinkageHuntington DiseaseLinkage AnalysisNeurodegenerative Disease GeneticsAssociation Between Linked Markers And TraitsFamilywise Error RateGene Mapping In FamiliesGene Mapping In PedigreesMultipoint Linkage AnalysisNeurodegenerative GeneticsPresymptomatic DiagnosisRecombination Fraction Estimation
To test the hypothesis that interfamily variability in Huntington's Disease (HD) is due to mutation at different loci, linkage analysis was undertaken in two large HD kindreds that differed in ethnicity, age-at-onset, and neurologic and psychiatric features. Both families showed linkage of the HD locus to the G8 probe. Several recombinants were documented in each family, and the best estimate of the recombination fraction for the two families was 6 percent with a 95 percent confidence interval of 0 to 12 percent. Although the data support the existence of a single HD locus, use of the G8 probe for presymptomatic testing in these kindreds would have resulted in a 12 percent error rate in genotype assignment at the HD locus.
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A polymorphic DNA marker genetically linked to Huntington's disease
James F. Gusella, Nancy S. Wexler, P. Michael Conneally et al. · Nature · 1983 · 2.3K citations